Survival over 2 years of autosomal-recessive renal tubular dysgenesis

نویسندگان

  • Su Yeong Kim
  • Hee Gyung Kang
  • Ee Kyung Kim
  • Jung Hwan Choi
  • Yong Choi
  • Hae Il Cheong
چکیده

Autosomal-recessive renal tubular dysgenesis (AR-RTD) is a rare disorder caused by a genetic defect in the renin-angiotensin system. Although AR-RTD has typically been known as a lethal disease due to refractory hypotension and renal failure immediately after birth, few cases have reported survival of the neonatal period. We report here an additional case of AR-RTD, who had novel ACE mutations and survived over 2 years and provide a review of the five previously reported surviving cases. In conclusion, AR-RTD is not a uniformly fatal disease, although factors affecting the survival remain unknown.

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عنوان ژورنال:

دوره 5  شماره 

صفحات  -

تاریخ انتشار 2012